Xeroderma pigmentosum group C in a French Caucasian patient with multiple melanoma and unusual long-term survival |
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Authors: | Jacobelli S Soufir N Lacapere J J Regnier S Bourillon A Grandchamp B Hétet G Pham D Palangie A Avril M F Dupin N Sarasin A Gorin I |
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Affiliation: | Department of Dermatology, Tarnier-Cochin Hospital APHP, UPRES EA1833, Faculty of Medicine Paris 5, 89 rue d'Assas, 75006 Paris, France. s.jacobelli@voila.fr |
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Abstract: | We report the case of an 83-year-old French woman with multiple melanomas showing a severe DNA repair deficiency, corrected after transfection by XPC cDNA. Two biallelic mutations in the XPC gene are reported: an inactivating frameshift mutation in exon 15 (c.2544delG, p.W848X) and a missense mutation in exon 11 (c.2108 C>T, P703L). We demonstrate that these new mutations are involved in the DNA repair deficiency and confirm the diagnosis of xeroderma pigmentosum from complementation group C (XP-C). We speculate that the coexistence of a MC1R variant may be involved in the phenotype of multiple melanomas and that the unusual long-term survival may be related to a lower ultraviolet radiation exposure and to a regular clinical follow-up. This patient appears to be the first French Caucasian XP-C case and one of the oldest living patients with XP reported worldwide. |
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Keywords: | gene mutation melanoma survival xeroderma pigmentosum XPC gene |
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